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J Autism Dev Disord (2016) 46:2275–2284

DOI 10.1007/s10803-016-2755-z

ORIGINAL PAPER

Comparison of a Self-Directed and Therapist-Assisted Telehealth


Parent-Mediated Intervention for Children with ASD: A Pilot
RCT
Brooke Ingersoll1 • Allison L. Wainer1,2 • Natalie I. Berger1 • Katherine E. Pickard1 •

Nicole Bonter1

Published online: 27 February 2016


Ó Springer Science+Business Media New York 2016

Abstract This pilot RCT compared the effect of a self- intensive and comprehensive intervention across the life
directed and therapist-assisted telehealth-based parent- span (National Research Council 2001). There has been a
mediated intervention for young children with ASD. dramatic increase in the number of individuals with this
Families were randomly assigned to a self-directed or diagnosis over the last two decades (Fombonne 2009)
therapist-assisted program. Parents in both groups without a corresponding growth in the availability of evi-
improved their intervention fidelity, self-efficacy, stress, dence-based intervention services, which has contributed to
and positive perceptions of their child; however, the ther- high levels of unmet service needs for individuals with
apist-assisted group had greater gains in parent fidelity and ASD and their families (Bitterman et al. 2008; Kogan et al.
positive perceptions of child. Children in both groups 2008). Thus, systematic research examining strategies for
improved on language measures, with a trend towards increasing access to evidence-based ASD services is a high
greater gains during a parent–child interaction for the priority.
therapist-assisted group. Only the children in the therapist- Parent-mediated intervention (PMI) programs are one
assisted group improved in social skills. Both models show potentially cost-effective strategy to increase access to
promise for delivering parent-mediated intervention; how- evidence-based ASD intervention. Teaching parents to
ever, therapist assistance provided an added benefit for provide intervention themselves can increase the number of
some outcomes. A full-scale comparative efficacy trial is intervention hours a child receives and has been shown to
warranted. result in improvements in child social-communication
skills (e.g., Kasari et al. 2015; Wetherby et al. 2014) and
Keywords Autism  Parent training  Telehealth parent well-being (Keen et al. 2010). Yet, formal PMI
programs are rare in community-based settings for young
children with ASD (Thomas et al. 2007a, b). Barriers
Introduction include a shortage of trained professionals, lengthy wait-
lists, limited financial resources and transportation, lack of
Autism spectrum disorder (ASD) is characterized by per- child care, geographic isolation, and time limitations (Sy-
vasive deficits in social communication and the presence of mon 2005). Thus, it is essential to consider the adaptation
restricted and repetitive behaviors (American Psychiatric of evidence-based PMI to non-traditional service delivery
Association 2013). Individuals with ASD often require models.
Telehealth, or the provision of health services and
information over the Internet and related technologies, has
& Brooke Ingersoll the potential to replace or augment traditional service
ingers19@msu.edu
models to increase access to evidence-based intervention
1
Department of Psychology, Michigan State University, 316 (Baggett et al. 2010; United States Department of Educa-
Physics Rd., East Lansing, MI 48824, USA tion, Office of Planning, Evaluation, and Policy Develop-
2
Present Address: Rush University Medical Center, Chicago, ment 2010). Telehealth programs can reduce costs and
IL, USA increase provider system coverage relative to traditional in-

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2276 J Autism Dev Disord (2016) 46:2275–2284

person service delivery models (Gros et al. 2013). Such colleagues examined the ability of a DVD-based (n = 8) or
programs have improved care for patients with chronic web-based tutorial (n = 9) in conjunction with weekly
diseases (Wootton 2012), and increased access to evidence- coaching sessions via video-conferencing to teach parents
based health promotion, psychological, and parenting to use the Early Start Denver Model (ESDM) (Vismara
interventions (e.g., Andersson and Cuijpers 2009; Krebs et al. 2012, 2013). Parents in both studies increased their
et al. 2010; Nieuwboer et al. 2013). Patients report high use of the ESDM intervention strategies and positively
levels of satisfaction with care received via telehealth altered their engagement styles during parent–child inter-
(Gustke et al. 2000) and efficacy studies have found actions in response to the program. Furthermore, their
moderate to large effects of telehealth interventions on children demonstrated gains in functional verbal utterances
participant knowledge and behavior change (Andersson and imitative play actions. To evaluate the relative con-
and Cuijpers; Krebs et al.; Nieuwboer et al. 2013). Further, tributions of self-directed instruction and therapist assis-
several meta-analyses have found that cognitive behavioral tance on parent learning, Wainer and Ingersoll (2015)
therapy (CBT) delivered via telehealth is as effective as conducted a second study (n = 5) that measured parents’
traditional therapy (Andrews et al. 2010). use of RIT at baseline, after a self-directed web-based
Telehealth interventions can be either self-directed (i.e., tutorial, and then again after receiving coaching via video-
participant independently engages with the interactive conferencing. Similar to their previous study (Wainer and
program) or therapist-assisted (i.e., participant receives Ingersoll 2013), all parents improved their use of RIT
additional guidance from a professional as part of the strategies during parent–child interactions in response to
program). Self-directed programs have greater dissemina- the self-directed program, but roughly a third showed
tion potential as they do not require a trained professional additional benefit from remote coaching. In addition, most
and can typically be administered at a reduced cost. children demonstrated gains in imitative play with the
However, therapist-assisted CBT telehealth programs typ- onset of treatment; however, child gains were most robust
ically lead to better patient outcomes than self-directed when parents received coaching.
programs (Andersson and Cuijpers 2009; Spek et al. 2007). These preliminary findings suggest telehealth PMI pro-
This finding may be particularly relevant for telehealth grams are acceptable to parents of children with ASD, and
PMIs, as research suggests that parent coaching is impor- can improve parent knowledge and intervention use and
tant for increasing parents’ fidelity of implementation child social communication skills. To date, no studies have
(Kaminski et al. 2008). conducted a head-to-head comparison of self-directed and
Empirical evaluations of telehealth PMI programs for therapist-assisted telehealth PMI. Data thus far suggest
children with ASD are limited. Several uncontrolled stud- therapist assistance may be necessary for some, but not all
ies have demonstrated the feasibility, acceptability, and parents to implement interventions with fidelity. A better
initial effectiveness (i.e., gains in parent knowledge) of understanding of the contributions of self-directed
self-directed telehealth PMI programs (Hamad et al. 2010; instruction and therapist assistance will make it possible to
Jang et al. 2012; Kobak et al. 2011). A small RCT (n = 27) develop more cost-effective delivery models in which
found that parents who received a DVD-based self-directed services are offered at different levels of intensity,
program made greater gains in their use of pivotal response depending on family needs (i.e., stepped-care) (Phaneuf
treatment (PRT) strategies, provided more language and McIntyre 2011; Steever 2011). Pilot studies enhance
opportunities, and were rated as displaying greater parent the likelihood of success of randomized controlled trials
confidence during a 10-min parent–child observation in the (RCT) (e.g., Campbell et al. 2007). Thus, the goal of this
home than parents in a no-treatment control group (Nefdt pilot study was to compare the effect of self-directed and
et al. 2009). In addition, their children demonstrated therapist-assisted delivery models of ImPACT Online, a
greater gains in their rate of functional verbal utterances telehealth PMI program that targets social communication
during the parent–child interaction. A single-case design using a naturalistic, developmental-behavioral intervention
study (n = 3) demonstrated that parents improved their use (NDBI) (Schreibman et al. 2015), on key parent and child
of reciprocal imitation training (RIT) strategies after outcomes in preparation for a fully powered RCT.
completing a web-based self-directed program (Wainer and
Ingersoll 2013), and their children increased their rate of
imitative toy play during parent–child interactions. Method
Importantly, parents in both studies indicated that coaching
from a professional would have been beneficial. Participants
Several single-case design studies have examined the
efficacy of therapist-assisted telehealth PMI programs for Twenty-eight families of a child with ASD between the
children with ASD. Across two studies, Vismara and ages of 19 and 73 months participated. Participants were

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J Autism Dev Disord (2016) 46:2275–2284 2277

recruited from agencies serving children with ASD. All therapist-assisted group (n = 14) using a coin flip.
children met criteria for Autistic Disorder or PDD-NOS Assessments were re-administered at post-treatment and
based on DSM-IV criteria (American Psychiatric Associ- 3-month follow-up in the family home. See Table 1 for
ation 2000) and the ADOS-G or ADOS-2 (Lord et al. participant flow through the study.
2000). Parents had to be proficient in English, although
other languages could be spoken in the home. One family Eligibility and Sample Characteristics Measures
who was assigned to the therapist-assisted group had to
suspend treatment after 2 months due to significant health Parents provided information on family and child demo-
problems. After a 7-month break, the family finished the graphics at pre-treatment. They also provided information
program; however, the time between their pre- and post- on hours per week of all non-study treatments at pre- and
treatment assessments (14 months) was not comparable to post-treatment. Children were administered the ADOS-G
the other participants’. Thus, their data were not included or ADOS-2 to determine study eligibility and the MSEL as
in the analyses. All parents gave informed consent under a measure of developmental functioning. See Table 2 for
the oversight of Michigan State University’s IRB. participant demographic information.

Design and Procedure Parent Outcomes Measures

Families were administered standardized assessments at Parent Intervention Fidelity


pre-treatment in the lab and family home. Children were
matched within 3 months on expressive language age on Parents were videotaped during a parent–child interaction
the Mullen Scales of Early Learning (MSEL; Mullen 1995) (PCI) in the family home at pre-treatment, post-treatment,
and randomly assigned to the self-directed (n = 13) or and 3-month follow-up. They were asked to: (1) play with

Table 1 Participant flow


through the study Enrollment
Assessed for eligibility (n=29)

Excluded (n=1)
Not meeting inclusion criteria (n=1)
Declined to participate (n=0)
Other reasons (n=0)

Randomized (n=28)

Allocation
Allocated to self-directed group (n=13) Allocated to therapist-assisted group (n=15)
Received allocated intervention (n=13) Received allocated intervention (n=15)
Did not receive allocated intervention (n=0) Did not receive allocated intervention (n=0)

Follow-Up
Lost to follow-up (n=0) Lost to follow-up (n=0)
Discontinued intervention (did not have time; Discontinued intervention (n=0)
family crisis; began intensive program) (n=4)

Analysis
Analysed (n=13) Analysed (n=14)
Excluded from analysis (n=0) Excluded from analysis (family took 14
months to complete due to crisis) (n=1)

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2278 J Autism Dev Disord (2016) 46:2275–2284

Table 2 Participant demographic information


Group Test statistic p value
Self-directed (n = 13) Therapist-assisted (n = 14)

Parent characteristics
Gender (% female) 92 % 100 % 1.12a .29
Education (% less than college degree) 54 % 36 % .90a .34
a
Marital status (% not married) 8% 29 % 1.95 .16
Employment status (% not employed) 46 % 29 % .65a .42
Residence in underserved area 77 % 64 % .52a .47
Child characteristics
Gender (% female) 39 % 21 % .94a .33
a
Race/ethnicity (% minority) 8% 36 % 3.06 .08
Chronological age (Mos.) 46.08 (13.18) 41.57 (12.24) -.71b .48
Nonverbal mental age (Mos.) 25.42 (13.92) 24.29 (9.38) -.25b .80
Verbal mental age (Mos.) 19.15 (9.63) 21.64 (10.74) .63b .53
Outside intervention (Hrs/wk)c 13.62 (10.96) 12.38 (9.70) -.31b .76
a
Chi-square
b
t test
c
Average of hours received at pre- and post-treatment

their child for 10 min; and (2) have a snack with their imputed by using the participant’s average for the scale.
child. Parent behavior was scored for correct use of the Cronbach’s alphas ranged from .86 to .92 for the parenting
intervention using the Project ImPACT fidelity checklist stress items and from .81 to .86 for the positive impact
(Ingersoll and Dvortcsak 2010). Fidelity ratings for the subscale.
play and snack routines were averaged to form an overall
fidelity rating for each time point. Reliability was calcu- Child Outcome Measures
lated for 20 % of the observations using intra-class corre-
lation (ICC = .96, p \ .001). Language Targets

Parent Sense of Competence Scale (PSOC) The children’s use of language targets was scored during
the PCI at pre, post, and follow-up. Language that was at or
Parents completed the PSOC (Gibaud-Wallston and Wan- above the child’s targeted language level and used appro-
dersmann 1978) at pre- and post-treatment as a measure of priately was scored using frequency counts and converted
parent self-efficacy. Parents rated items from 1 (‘‘Strongly to rate per minute. Language targets were determined at
agree’’) to 6 (‘‘Strongly disagree’’) with higher scores intake based on the child’s spontaneous language during
indicative of higher parenting self-efficacy. Missing item standardized and observational assessments using Tager-
level data (\5 %) were imputed by using the participant’s Flusberg et al. (2009) framework for defining spoken lan-
average for the scale. Cronbach’s alpha was .85. guage benchmarks for children with ASD. Language acts
were scored if they were at or above the child’s current
Family Impact Questionnaire (FIQ) expressive language phase, which included word approxi-
mations for children at the preverbal communication stage,
Parents completed the FIQ (Donenberg and Baker 1993) at single words for children at the first words stage, phrase
pre- and post-treatment as a measure of the impact of their speech for children at the word combinations stage, and
child on their family life. Parents endorse items on a grammatically correct sentences for children at the sen-
4-point scale, with higher scores indicating greater impact. tences stage. Both prompted and spontaneous use of lan-
The average of the negative and social impact subscales guage targets was scored. Data from the play and snack
was used as a measure of parenting stress, and the positive routines were averaged to form an overall rate of language
impact subscale was used as the measure of positive per- targets for each time point. Reliability was calculated for
ceptions of the child. Missing item level data (\5 %) were 25 % of the observations (ICC = .98, p \ .001).

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J Autism Dev Disord (2016) 46:2275–2284 2279

MacArthur-Bates Communicative Development Inventory Group Assignment


(MCDI)
Self-Directed Group
Parents completed the MCDI at pre and post as a measure
of their child’s expressive vocabulary (Fenson et al. 2006). The self-directed group received access to the secure,
The total number of words reported as ‘‘understands and password-protected, ImPACT Online website for
says’’ (Words and Gestures Form) or ‘‘words produced’’ 6 months. The content was adapted from Project ImPACT
(Word and Sentences Form) was used. Test–retest relia- (Ingersoll and Dvortcsak 2010), a NDBI-based PMI for
bility of the MCDI is .95 (Fenson et al. 1994). The MCDI young children with ASD targeting social communication
was missing at pre-treatment for one participant. development. The website contained 12, self-directed les-
sons; each took approximately 75 min to complete. Parents
Vineland Adaptive Behavior Scales, Second Edition were encouraged to complete one lesson per week and to
(VABS-II) practice the intervention with their child between each
lesson. Parents were able to contact project staff for
Parents were interviewed on the VABS-II at pre and post assistance with technology-related problems, but received
(Sparrow et al. 2005). The VABS-II is a standardized no staff support in learning the intervention. See Table 3
parent interview that assesses child adaptive functioning in for description of the ImPACT Online program
four domains: Communication, Socialization, Daily Living components.
Skills, and Motor Skills. Each domain yields a standard
score with a mean of 100 and a standard deviation of 15. Therapist-Assisted Group
Test–retest reliability estimates range from .88 to .92 for
the domain scores. Given the focus of ImPACT Online The therapist-assisted group was given access to the
(social communication development), we expected ImPACT Online website for 6 months and was encouraged
improvement in standard scores on the Social and Com- to work through the program at the same pace as the self-
munication domains indicating accelerated development. directed group. These parents also received 2, 30 min
As a comparison, we examined changes on the Daily coaching sessions per week (24 total) from a trained ther-
Living and Motor Skills domains, with no expectation for apist via video-conferencing. The first coaching session of
improvement. The VABS was missing at post-treatment for each week was used to clarify the lesson content and help
one participant. parents apply the information to their child. The second

Table 3 ImPACT online program components


Primary lesson components
Slideshow Users watch narrated slideshow with embedded video examples of techniques
Manual Users read the manual which provides a written description of lesson that corresponds to slideshow
Self-check Users answer comprehension check questions based on content of slideshow. The program provides automated positive
and corrective feedback
Exercises Users observe brief video clips and must indicate whether technique is implemented correctly or incorrectly. The
program provides automated positive and corrective feedback
Homework Users complete a homework plan that outlines techniques and activities in which to practice. These responses are
available to the coach for the therapist-assisted group
Reflection Users complete reflection questions based on their practice. These responses are available to the coach for the therapist-
assisted group
Supplemental components
Video library Users can observe longer videos of adults using the intervention techniques together with children at different language
levels
Forum Users can share information with other participants and post content-related questions and receive feedback from project
staff
Resources Users can access paper copies of all forms, additional information on the evidence-base for this intervention, and links to
relevant websites
Tip of the week Users receive weekly ‘‘Tip of the Week’’ emails that provide tips for implementing the intervention techniques along
Emails with a link to the program

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session of the week was used to provide parents with live data from the 23 parents who completed the program. For
feedback on their intervention use with their child. these data, we conducted a completer analysis only.
Coaching was provided by masters’ level therapists trained Transformations were applied to non-normal data as
to fidelity. Coaches used a fidelity checklist to rate their appropriate. VABS-II data remained non-normal after
fidelity to the coaching procedure at the end of each ses- multiple transformation attempts, potentially due to out-
sion. Average self-assessed fidelity across sessions was liers. We report analyses for the VABS-II with non-normal
99.6 %. A random sample of 10 % of coaching sessions data as ANOVA is robust to this violation.
were scored by independent raters for reliability using Independent t tests and Chi-square tests revealed no
exact agreement. Reliability for coaching fidelity was statistically significant group differences on any pre-treat-
97.8 %. ment variables, although a marginally significant group
difference (p = .08) was observed in the percent of chil-
dren who were minorities. To determine the effect of the
Results intervention on parent and child outcomes, we conducted a
series of mixed-model repeated measures ANOVAs with
Analytic Strategy time (pre, post) as the within group variable and group
(self-directed, therapist-assisted) as the between group
We used an Intention-to-Treat model (ITT) which requires variable. We conducted a second set of mixed-model
that all randomly assigned participants be compared on repeated measures ANOVAs on the follow-up PCI data
outcomes regardless of adherence to treatment, reasons for with time (pre, follow-up) and group as the within and
withdrawal, or missing responses (Moher et al. 2001). between group variables. Post hoc comparisons of simple
Accordingly, we included all participants in the data effects of significant interactions were conducted using
analysis, followed up participants who discontinued treat- relevant t tests. See Table 4 for ANOVA results for out-
ment, and imputed missing data. Four parents, all in the come variables.
self-directed group, did not complete the program, which
represented a significant group difference in rate of pro- Parent Outcomes
gram completion, v2 (n = 27) = 5.06, p = .03. We
obtained post-treatment data for these families on all There was a significant main effect of time for parent
measures, with the exception of the VABS-II and PCI for fidelity, such that parents were rated higher on their use of
one family. The MCDI was missing for one child in the the intervention at post-treatment. There was also a sig-
therapist-assisted group at pre-treatment. We used partici- nificant time X group interaction, indicating the therapist-
pants’ data from the opposite point of treatment for the assisted group made greater gains in fidelity than the self-
missing data point. We collected follow-up 3-month PCI directed group. Post-hoc tests of simple effects suggested

Table 4 ANOVA results for outcome variables


Outcome measure Self-directed group Therapist-assisted group Effects
Pre Post Pre Post Time Time X group
Mean (SD) Mean (SD) Mean (SD) Mean (SD) F (g2p) F (g2p)

Parent fidelity (PCI) 1.77 (.67) 2.52 (.78) 1.62 (.37) 3.39 (.76) 65.78** (.72) 10.76** (.30)
Parent self-efficacy (PSOC) 53.23 (13.14) 58.62 (12.12) 54.60 (14.81) 61.43 (13.27) 10.98** (.31) .15 (.006)
Parenting stress (FIQ) 1.24 (.84) 1.04 (.61) 1.02 (.46) .69 (.30) 6.53* (.21) 2.18 (.08)
Parent positive perceptions (FIQ) 1.52 (.58) 1.60 (.50) 1.40 (.72) 2.06 (.56) 13.31** (.35) 8.27** (.25)
Child language targets (PCI) 1.36 (1.53) 1.95 (1.08) .65 (.52) 1.80 (1.00) 31.33** (.56) 2.84? (.10)
Child vocabulary (MCDI) 144.69 (146.21) 210.38 (187.46) 185.114 (202.17) 243.64 (237.94) 18.53** (.43) 1.17 (.05)
Child communication (VABS-II) 71.50 (15.57) 75.33 (12.40) 70.29 (11.28) 77.36 (13.79) 6.10* (.20) .68 (.03)
Child social skills (VABS-II) 71.00 (8.05) 70 .00 (7.56) 70.00 (6.95) 75.71 (9.07) 2.58 (.09) 4.94* (.17)
Child daily living skills (VABS- 74.77 (13.79) 74.23 (10.42) 75.07 (7.77) 77.00 (11.14) .26 (.01) .83 (.03)
II)
Child motor skills (VABS-II) 81.85 (11.47) 82.85 (9.74) 83.36 (8.87) 83.14 (11.27) .08 (.003) .18 (.007)
?
** \.01; * \.05; .10

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both groups had higher fidelity ratings at post- than pre- On the MCDI and VABS-II Communication domain,
treatment (ps \ .01), and at post-treatment, the therapist- there was a main effect of time, but no effect of group or
assisted group was significantly higher than the self-di- time X group interaction, suggesting that children in both
rected group (p \ .01). At follow-up, there was a signifi- groups improved their language skills on these measures
cant main effect of time, F(1, 21) = 44.26, p \ .001, from pre- to post-treatment. On the VABS-II Social
g2p = .68, suggesting that the benefits of the program on domain, there were no main effects of time or group;
parent fidelity maintained. The time X group interaction however, there was a significant time X group interaction.
was not significant, F(1, 21) = 1.17, p = .29, g2p = .05, Post-hoc tests suggested that the children in the therapist-
suggesting that the therapist-assisted group (M = 3.00, assisted group exhibited significant increases in their
SD = .66) no longer showed an advantage over the self- standard scores (p = .04), while the children in the self-
directed group (M = 2.57, SD = 1.21) at follow-up, directed group did not. At post-treatment, the therapist-
although their mean fidelity ratings remained higher. assisted group had marginally higher standard scores than
There was a significant main effect of time on parent the self-directed group (p = .08).
self-efficacy, such that parents in both groups rated them- No significant main effects of time or group and no
selves as more efficacious at post-treatment. There was no significant time X group interactions were observed for the
significant effect of group or time X group interaction. VABS-II Daily Living or Motor Skills domains.
There was a main effect of time on parenting stress, such
that parents in both groups rated themselves as less stressed
at post-treatment, but no significant main effect of group or Discussion
time X group interaction. Finally, there was a significant
main effect of time and time X group interaction for pos- This pilot RCT compared the effect of a self-directed and a
itive perceptions of the child. Post-hoc tests suggested that therapist-assisted telehealth PMI for children with ASD on
the therapist-assisted group had significant (p = .001) and parent and child outcomes. Parents in both groups
the self-directed group had marginally significant (p = .09) improved their fidelity. This finding suggests the self-di-
increases in their positive perceptions of their child, and the rected website was sufficient for increasing parent inter-
therapist-assisted group had significantly more positive vention use and provides additional support for the benefits
perceptions than the self-directed group at post-treatment of self-directed telehealth programs for increasing parents’
(p = .03). skills (Nefdt et al. 2009; Wainer and Ingersoll 2013).
However, parents in the therapist-assisted group made
Child Outcomes greater gains in their use of the intervention. Similar
findings were observed regarding parents’ perceptions of
There was a significant main effect of time on language their child; parents in the therapist-assisted group had
targets during the PCI, indicating improvement in child greater increases in their positive perceptions of their child
language use over time. There was also a marginally sig- than the self-directed group.
nificant time X group interaction (p = .10), suggesting that These findings are consistent with research on the ben-
the children in the therapist-assisted group made margin- efits of coaching in traditional PMI (Kaminski et al. 2008),
ally more gains in their use of language targets than the and suggest that coaching may be important for maximiz-
self-directed group. Post-hoc tests indicated children in ing parent gains from telehealth PMI as well. Coaching
both groups exhibited significant gains in their language provides parents with feedback on their intervention use
targets from pre- to post-treatment (ps \ .05), but there and highlights its impact on their child’s behavior. Parents
were no differences between groups at post-treatment. At who received coaching likely thus developed a greater
follow-up, there was a significant main effect of time on understanding of their child’s skills and a better apprecia-
child language targets, F(1, 21) = 8.59, p = .008, tion for the impact of their own behavior on their child’s,
g2p = .29, and a marginally significant time X group potentially improving their positive perceptions of their
interaction, F(1, 21) = 3.38, p = .08, g2p = .14. Post-hoc child. Higher rates of program completion among the
tests indicated language targets were higher at follow-up therapist-assisted group may also have contributed to
(M = 1.71, SD = 1.28) than pre-treatment for the thera- observed group differences. Indeed, these parents were
pist-assisted group (p = .003). The difference in language significantly more likely to complete the program (100 %)
targets from pre-treatment (M = 1.50, SD = 1.81) to fol- than parents in the self-directed group (69 %). Thus,
low-up (M = 1.64, SD = 1.21) was not significant for the therapist assistance may be important not only for pro-
self-directed group, although the trend was in the expected viding parents with feedback on their use of the interven-
direction. There were no group differences in language tion and highlighting child skills, but also for encouraging
targets at follow-up. higher levels of engagement with the program in general,

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both of which may influence parent fidelity and/or positive limited power may have contributed to our failure to
child perceptions. Given that program completion was identify group differences in treatment response for several
related to increases in parent fidelity (Ingersoll and Berger of our outcome measures. For example, despite not
2015), this is a distinct possibility. Either way, there reaching significance, the effect sizes for the time X group
appears to be a benefit of therapist assistance on these two interactions for parenting stress (g2p = .08) and child lan-
parent outcomes. Additional research that can examine guage targets (g2p = .10) were in the moderate range,
which aspects of therapist assistance are most important suggesting that with a larger sample size, these interactions
would be beneficial. would likely have become significant. A power analysis
Improvements were also observed for parent self-effi- suggested that we would have needed a sample size of 60
cacy and parenting stress. This finding is important as to detect significant differences for effect sizes in this
parents of children with ASD often experience lower self- range.
efficacy and higher stress than other parents (Hayes and In addition, while we were able to establish an effect of
Watson 2013), and both are related to parent well-being therapist assistance for those outcomes for which the
(Carter 2009; Karst and Hecke 2012). Interestingly, there therapist-assisted group demonstrated greater improvement
were no group differences in these parent outcomes. These than the self-directed group, without a no-treatment control
findings suggest that the self-directed program may be group, we cannot conclude that the improvements observed
sufficient for increasing parent well-being. Perhaps parents in the self-directed group were a result of treatment. Sim-
who receive instruction in strategies to help their child ilarly, we cannot rule out maturation or placebo effects for
experience a greater sense of empowerment or agency, those outcomes for which both groups improved to the
regardless of instructional format. Indeed, parent empow- same degree. We were, however, able to compare child
erment and agency are associated with greater self-efficacy changes across VABS-II domains. As predicted, we found
and lower parenting stress in families of children with ASD improvements for only those domains targeted by the
(Kuhn and Carter 2006). Future research that can identify program, suggesting that maturation or a placebo effect
those components most likely to improve parent self-effi- (i.e., parent reporting bias) were unlikely solely responsible
cacy and parenting stress would be informative. We also for gains in child skills. However, additional research that
found evidence for improvement in children’s social includes a web-based control is necessary to establish the
communication skills. Although the groups did not differ in effect of both formats on parent and child functioning.
the degree of improvement on the two parent-reported One additional limitation is that our treatment groups
language measures, the children in the therapist-assisted differed in number of children from minority backgrounds,
group made marginally greater gains in their language with a larger number of minority children in the therapist-
targets during the PCI than the self-directed group. These assisted group (36 %) than the self-directed group (8 %). It
findings suggest that both the self-directed and therapist- is not clear to what extent this might have impacted the
assisted formats may be effective for increasing child findings. Child minority status was not associated with rate
communication skills, although there may be a small of parent program engagement (Ingersoll and Berger 2015)
benefit of therapist assistance, as observed within the PCI. for either group. However, it is possible that it might
In contrast, only the therapist-assisted group made impact other aspects of the treatment process. Future
improvements in their social skills on the VABS-II. Studies research should examine the degree to which racial/ethnic
examining parent-mediated social communication inter- background and other demographic variables might affect
ventions for young children with ASD have more often treatment response.
reported improvements in child language than social skills These data contribute to the growing empirical support
(McConachie and Diggle 2007). Social skills may be less for the benefits of parent-mediated NDBIs on parent and
amenable to treatment than language, and as such, therapist child outcomes (Schreibman et al. 2015), and provide
assistance may be necessary to help parents improve their further support for the ability of telehealth to teach parents
child’s social development. For this study, we had only one to deliver these interventions (Nefdt et al. 2009; Vismara
broad measure of social skills. Thus, it is possible that we et al. 2013; Wainer and Ingersoll 2015). These pilot data
would have observed improvements in the self-directed suggest a potential role for both self-directed and therapist-
group as well, had we used a more sensitive measure or assisted programs for increasing parent access to evidence-
examined specific skills. Future research that can determine based interventions, and suggest the potential benefit of
which social skills are most responsive to the intervention, supplementing telehealth interventions with therapist sup-
as well as the potential benefit of the self-directed program port. In addition, these data strongly support conducting a
on specific social skills is necessary. fully powered comparative efficacy trial to examine
A major limitation to this study is the small sample size mediators and moderators of treatment. Such a study
inherent in a pilot study. Our small sample and resultant should identify which outcomes are best targeted by each

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format, as well as which parents and children benefit from Fombonne, E. (2009). Epidemiology of pervasive developmental
the different levels of care. The ultimate goal is to develop disorders. Pediatric Research, 65(6), 591–598.
Gibaud-Wallston, J., & Wandersmann, L. P. (1978). Development and
a stepped-care model that can increase access to evidence- utility of the parenting sense of competence scale. Washington:
based interventions, and reduce the high level of unmet John F. Kennedy Center for Research on Education and Human
needs experienced by families of children with ASD. Development.
Gros, D. F., Morland, L. A., Greene, C. J., Acierno, R., Strachan, M.,
Acknowledgments This project was supported by CDMRP Grant: Egede, L. E., & Frueh, B. C. (2013). Delivery of evidence-based
#W81XWH-10-1-0586. The first author receives royalties from the psychotherapy via video telehealth. Journal of Psychopathology
sale of the manual that was adapted for use in the online tutorial. and Behavioral Assessment, 35(4), 506–521.
Royalities are donated to the research. We thank the families who Gustke, S. S., Balch, D. C., West, V. L., & Rogers, L. O. (2000).
participated in this study. Patient satisfaction with telemedicine. Telemedicine Journal,
6(1), 5–13.
Author Contributions BI conceived of the study, participated in its Hamad, C. D., Serna, R. W., Morrison, L., & Fleming, R. (2010).
design and coordination and drafted the manuscript; ALW, NIB, and Extending the reach of early intervention training for practici-
KEP performed the measurement and participated in its design and tioners: A preliminary investigation of an online vurriculum for
coordination and helped to draft the manuscript. NB performed the teaching behavioral intervention knowledge in autism to families
measurement and participated in the study’s coordination. All authors and service providers. Infants and Young Children, 23(3),
read and approved the final manuscript. 195–208.
Hayes, S., & Watson, S. (2013). The impact of parenting stress: A meta-
analysis of studies comparing the experience of parenting stress in
parents of children with and without autism spectrum. Journal of
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